Pediatrics Residency Program
 
Diagnosis

Diagnosis of the HSANs depends primarily on clinical examinations and specific sensory and autonomic assessments. Pathologic examinations serve to further confirm differences. In recent years identification of specific genetic mutations for some disorders has aided diagnosis. Replacement or definitive therapies are not available for any of the disorders so that treatment remains supportive and directed toward specific symptoms.

The only diagnostic feature common to all HSAN is the absence of an axon flare following intradermal histamine. [HISTAMINE TESTS- Normal and FD responses]

If there is difficulty distinguishing between the HSAN using clinical signs, then sural nerve biopsy is suggested.

Clinical Feature
HSAN III
FD
HSAN IV
CIPA
HSAN II
CSN
CAD
Histamine test No axon flare No axon flare No axon flare No axon flare
Overflow tears No Yes Delayed Yes
Lingual fungiform Papillae No Yes No No
Deep tendon reflexes Absent Present Absent Absent
Sural Nerve Biopsy
       
Myelinated neurons Slight decrease Marked decrease Severe decrease Marked decrease
Unmyelinated neurons Severe decrease (25% of normal) Very severe decrease (5-10% of normal) Moderate decrease Slight decrease

 

FD: familial dysautonomia, CIPA: Congenital insensitivity to pain with anhidrosis,
CSN: Congenital sensory neuropathy, CAD: Congenital autonomic dysfunction with universal pain loss.